A recurrence odontogenic keratocyst formation of mandible with distinctive features: a case report

Introduction and importance: Odontogenic keratocyst is a distinctive form of developmental odontogenic cysts that deserves a special consideration because of its specific clinical behavior and histopathologic features. The clinical and radiographic features of OKC are indefinite; while some may be associated with pain, swelling or drainage, most of them are asymptomatic. This case reports a rare radiographic and histpathological features of recurrence OKC. Case Presentation: A 47-years-old male patient presented with a main complaint of painful mass in the oral cavity with a history of previous lesion occurred in the posterior portion of mandible related to extraction of impacted third molar. The oral examination revealed a swelling in molar region of right mandible with lingual plate expansion. The radiographic and histopathologic were consistent with the diagnosis of OKC. Consequently, the lesion was surgically removed with no clinical or radiological recurrence observed during the 8-months post-operative follow-up. Clinical Discussion This case explained the clinical differences between OKC and other lesions, and highlights the distinctive radiologic and microscopic features which make a confliction with previous studies, concerning the symptoms that may related to Nevoid Basal Cell Carcinoma Syndrome, and revealed the proper treatment depending on the recurrence appearance and the treatment methods that used previously. Conclusions This case highlights a rare multilocular appearance of recurrent OKC in mandible with no Nevoid Basal Cell Carcinoma Syndrome related, supports the marginal resection as an effective procedure in management of recurrent OKCs cases.