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September 10, 2025GenesOpen Access

Genotypic and Phenotypic Characterization of Axonal Charcot–Marie–Tooth Disease in Childhood: Identification of One Novel and Four Known Mutations

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Authors

RİRojan İpekBÇBüşra Eser ÇavdartepeSBSevcan Tuğ Bozdoğan

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Overview

Retrospective study identifies one novel and four known mutations in pediatric axonal CMT, highlighting clinical features and molecular diagnostics.

Key Points

  • Identification of a novel homozygous frameshift variant in the IGHMBP2 gene enhances understanding of axonal charcot-marie-tooth disease.
  • Among five pediatric patients, absent deep tendon reflexes and distal muscle weakness were consistently observed, with three exhibiting intellectual disability.
  • This study employed whole exome sequencing and gene panel testing to uncover mutations linked to various axonal cmt subtypes in pediatric patients.
  • The findings call for increased awareness of unique phenotypic associations, as seen with the MPV17 mutation's co-occurrence with congenital heart disease.

Cite This Study

İpek et al. (2025) studied this question.

synapsesocial.com/papers/68c19fa854b1d3bfb60db69dhttps://doi.org/10.3390/genes16080917
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