Case report describes a rare venous malformation in a neonate with a KRIT1 pathogenic variant, highlighting its cutaneous involvement.
Familial cerebral cavernous malformation (FCCM) is a rare autosomal dominant disorder marked by venous malformations of the central nervous system. Cutaneous involvement occurs in fewer than 10% of cases and typically presents as hyperkeratotic or angiokeratoma-like plaques, most often associated with pathogenic variants in KRIT1 , CCM2 , or PDCD10 . We describe a neonate from Northern New Mexico, where the KRIT1 Common Hispanic Pathogenic Variant (c.1363C>T, p.Gln455Ter) is highly prevalent, who presented at birth with a congenital, ulcerated segmental purpuric plaque and violaceous papules. Histopathology and GLUT1 positivity were consistent with a verrucous venous malformation within the phenotypic spectrum of FCCM. Targeted genetic testing confirmed a heterozygous KRIT1 variant. This case expands the cutaneous spectrum of FCCM and underscores the value of early molecular diagnosis in neonates with atypical vascular anomalies, especially in regions with a known founder effect.
No takes yet. Share an insight, caveat, or question.
Rizzo et al. (2025) studied this question.
Synapse has enriched 5 closely related papers on similar clinical questions. Consider them for comparative context: