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July 1, 1999Journal of Medical GeneticsOpen Access

Double heterozygosity for MYH7 and MYBPC3 mutations in familial hypertrophic cardiomyopathy is associated with significantly greater left ventricular hypertrophy than single mutations.

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Why the study?

Does double heterozygosity for MYH7 and MYBPC3 mutations result in a more severe phenotype in familial hypertrophic cardiomyopathy?

Population

15 subjects from a French Caribbean family, 8 of whom were affected with hypertrophic cardiomyopathy based…

Comparison

Double heterozygosity for mutations in the… vs Single mutation carriers within the same family.

Design

Case_series

Key result

Double heterozygosity for MYH7 and MYBPC3 mutations in familial hypertrophic cardiomyopathy is associated with significantly greater left ventricular hypertrophy than single mutations.

Authors

PRPascale RichardRIRichard IsnardLCLucie Carrier

Discussion

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Overview

Double heterozygosity for MYH7 and MYBPC3 mutations in familial hypertrophic cardiomyopathy is not lethal but is associated with a more severe phenotype of left ventricular hypertrophy.

Study Design

Type

Observational (n=15)

Multicenter

No

Structured PICO

Does double heterozygosity for MYH7 and MYBPC3 mutations result in a more severe phenotype in familial hypertrophic cardiomyopathy?

P
Population
15 subjects from a French Caribbean family, 8 of whom were affected with hypertrophic cardiomyopathy based on ECG and echocardiography.
I
Intervention
Double heterozygosity for mutations in the β-myosin heavy chain (MYH7) and cardiac myosin binding protein C (MYBPC3) genes.
C
Comparator
Single mutation carriers (MYH7 or MYBPC3) within the same family.
O
Outcome
Severity of left ventricular hypertrophy assessed by echocardiography.surrogate

Double heterozygosity for MYH7 and MYBPC3 mutations in familial hypertrophic cardiomyopathy is not lethal but is associated with a more severe phenotype of left ventricular hypertrophy.

Cite This Study

Richard et al. (1999) conducted an observational in Familial hypertrophic cardiomyopathy (n=15). Double heterozygosity for MYH7 and MYBPC3 mutations vs. Single mutation carriers was evaluated on Left ventricular hypertrophy severity. Double heterozygosity for MYH7 and MYBPC3 mutations in familial hypertrophic cardiomyopathy is associated with significantly greater left ventricular hypertrophy than single mutations.

synapsesocial.com/papers/6a1928ae2471b46e09d954f8https://doi.org/10.1136/jmg.36.7.542
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