Key result
Multigene panel testing identifies putative LQTS causes in ~10% of genotype-negative long QT patients.
Why the study?
Genetic causes of prolonged QTc intervals remain unclear in patients negative for pathogenic variants in the three major LQTS-related genes KCNQ1, KCNH2, and SCN5A.
Does multigene panel sequencing identify genetic causes in patients with prolonged QTc intervals who are negative for major LQTS-related genes?
Observational (n=30)
Does multigene panel sequencing identify genetic causes in patients with prolonged QTc intervals who are negative for major LQTS-related genes?
Multigene panel sequencing can identify putative genetic causes in approximately 10% of patients with prolonged QTc intervals who test negative for the three major LQTS genes.
May support expanded panels in unexplained QTc prolongation; hypothesis-generating and should not yet change practice.
Long QT syndrome (LQTS) is an inherited cardiac disease characterized by a prolonged heart rate-corrected QT (QTc) interval. We investigated the genetic causes in patients with prolonged QTc intervals who were negative for pathogenic variants in three major LQTS-related genes (KCNQ1, KCNH2, and SCN5A). Molecular genetic testing was performed using a panel including 13 LQTS-related genes and 67 additional genes implicated in other cardiac diseases. Overall, putative genetic causes of prolonged QTc interval were identified in three of the 30 patients (10%). Among the LQTS-related genes, we detected a previously reported pathogenic variant, CACNA1C c.1552C>T, responsible for cardiac-only Timothy syndrome. Among the genes related to other cardiac diseases, a likely pathogenic variant, RYR2 c.11995A>G, was identified in a patient with catecholaminergic polymorphic ventricular tachycardia. Another patient who developed dilated cardiomyopathy with prolonged QTc interval was found to carry a likely pathogenic variant, TAZ c.718G>A, associated with infantile dilated cardiomyopathy. Comprehensive screening of genetic variants using multigene panel sequencing enables detection of genetic variants with a possible involvement in QTc interval prolongation, thus uncovering unknown molecular mechanisms underlying LQTS.
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Seo et al. (2017) conducted an observational in Prolonged rate-corrected QT interval (n=30). Multigene panel sequencing was evaluated on Identification of putative genetic causes of prolonged QTc interval. Multigene panel sequencing identified putative genetic causes of prolonged QTc interval in 10% (3 of 30) of patients negative for pathogenic variants in major LQTS-related genes.
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